Cutaneous Sarcoidosis

Sarcoidosis is a multisystem granulomatous disease characterized by noncaseating granulomas. Cutaneous sarcoidosis occurs in up to one-third of patients and may be the initial or sole manifestation. Skin lesions are polymorphic, including papules/plaques, lupus pernio, scar or tattoo infiltration, subcutaneous nodules, and erythema nodosum (a reactive, non-specific lesion). Cutaneous disease can correlate with systemic involvement and chronicity. Diagnosis requires clinicopathologic correlation and exclusion of infections and foreign-body granulomatous reactions. Management ranges from topical/intralesional corticosteroids to systemic immunomodulators for extensive, disfiguring, or refractory disease.

Epidemiology

  • Variable incidence; higher in people of African or Northern European ancestry; female predominance in some cohorts.
  • Onset typically young to middle adulthood.
  • Cutaneous phenotypes may predict systemic course: lupus pernio associated with chronic upper airway/pulmonary disease.

Pathophysiology

  • Dysregulated cell-mediated immunity with Th1/Th17 skewing; macrophage epithelioid granuloma formation.
  • Genetic susceptibility (e.g., BTNL2, HLA alleles); environmental/occupational exposures implicated.
  • Triggering by cutaneous injury: scar/tattoo sarcoidosis.

Clinical Features

  • Specific sarcoidosis lesions (granulomas on biopsy):
    • Papular sarcoidosis: small red-brown papules, often periorificial or on face.
    • Plaque sarcoidosis: infiltrated plaques; annular or serpiginous variants.
    • Lupus pernio: violaceous indurated plaques on nose, cheeks, ears; chronic and disfiguring.
    • Scar/tattoo sarcoidosis: granulomatous infiltration of prior scars/ink.
    • Subcutaneous sarcoidosis (Darier–Roussy): firm nodules on extremities/trunk.
  • Nonspecific lesions:
    • Erythema nodosum: tender septal panniculitis, typically on shins; part of Löfgren syndrome (EN, bilateral hilar adenopathy, arthritis) with good prognosis.
  • Other clues: apple-jelly translucency on diascopy; anhidrosis, alopecia in involved areas.

Differential Diagnosis

  • Granulomatous infections: cutaneous TB, atypical mycobacteria, deep fungal infections (histoplasmosis, blastomycosis).
  • Granuloma annulare, necrobiosis lipoidica, foreign body reactions, lupus vulgaris, leprosy, rosacea (for facial lesions).

Diagnostic Workup

  • Skin biopsy: noncaseating epithelioid granulomas with sparse lymphocytic infiltrate; special stains and cultures to exclude infections (AFB, PAS/GMS).
  • Assess systemic involvement:
    • Chest imaging (CXR or HRCT) for hilar/mediastinal adenopathy or parenchymal disease.
    • Serum ACE (nonspecific), calcium (hypercalcemia/hypercalciuria), CBC/CMP.
    • Organ-directed assessments as indicated: ophthalmology (uveitis), PFTs, ECG; consider PET-CT for extent in refractory/systemic disease.
  • Review occupational/environmental exposures; check for foreign material in lesions (polarization).

Management

  1. Localized cutaneous disease
  • High-potency topical corticosteroids; intralesional triamcinolone for plaques, lupus pernio, and scar lesions.
  • Topical calcineurin inhibitors as adjuncts in sensitive areas.
  1. Extensive/disfiguring or refractory cutaneous disease, or significant systemic involvement
  • Systemic corticosteroids are first-line for rapid control.
  • Steroid-sparing agents: methotrexate (most evidence), hydroxychloroquine or chloroquine (especially for cutaneous disease and hypercalcemia), leflunomide, azathioprine, mycophenolate.
  • Biologics for refractory cases: TNF-α inhibitors (infliximab, adalimumab) have supportive data in cutaneous and systemic sarcoidosis, including lupus pernio.
  • Emerging/adjunctive: JAK inhibitors reported in refractory sarcoidosis; tetracyclines (anti-granulomatous), minocycline/doxycycline; thalidomide for stubborn cutaneous lesions.
  1. Erythema nodosum (nonspecific)
  • Treat underlying sarcoidosis; symptomatic therapy with NSAIDs, rest, compression; short steroid course for severe pain.

Prognosis and Monitoring

  • Many patients experience chronic or relapsing disease; lupus pernio indicates persistent course and may require aggressive therapy.
  • Monitor for systemic organ involvement over time; ophthalmologic exams are important.
  • Track steroid-sparing strategy to minimize long-term corticosteroid toxicity.

References (recent guidelines and key reviews)

  • ERS/ATS/WASOG statements on sarcoidosis diagnosis and management, 2021–2024 updates.
  • Dermatology-focused reviews of cutaneous sarcoidosis and treatment algorithms, 2022–2024.
  • Evidence for TNF inhibitors and methotrexate in sarcoidosis (systematic reviews, 2021–2024).
  • Case series and reports on JAK inhibitors in refractory sarcoidosis, 2022–2024.

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